mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

5
Case report Mixed epithelial and stromal tumor of the kidney with polypoid component extending into renal pelvis and ureter Masahiro Horikawa 1 , Hiroshi Shinmoto 1 , Kenji Kuroda 2 , Eisuke Shiomi 1 , Shigeyoshi Soga 1 , Keiichi Ito 2 , Kazuyoshi Tachi 2 , Yuka Katsurada 3 , Hideyuki Simazaki 3 , Tomohiko Asano 2 and Tatsumi Kaji 1 1 Department of Radiology; 2 Department of Urology; 3 Department of Laboratory Medicine, National Defense Medical College, Saitama, Japan Correspondence to: Masahiro Horikawa. Email: [email protected]  Abstra ct Mixed epithelial and stromal tumor (MEST) of the kidney is an unusual benign neoplasm that predominantly occurs in middle-aged females. It typically appears as a well-circumscribed multiseptate mass with solid components on computed tomography (CT) or magnetic resonance image (MRI), reecting its characteristics of an admixture of stromal proliferation and epithelial cells consisting of multiple cysts. We present a rare case of 61-year-old woman with MEST, which manifested as a multilocular cystic mass with a polypoid component protruding into the renal pelvis and ureter. To our best knowledge, this is the rst case of MEST extending into the ureter. Keywords: Mixed epithelial and stromal tumor, MEST, kidney, ureter, CT, MRI Submitted October 26, 2011; accepted for publication November 24, 2011 Mixed epithelial and stromal tumor (MEST) is a rare, basi- ca lly be nig n neoplas m of the ki dney tha t has re cent ly been recognized as a distinctive entity (1). It mostly occurs in middle -aged women and is associate d with es tro gen exposure (2). The histological characteristic of MEST is an admixture of spindle cells resembling ovarian stroma and epi thel ial ele men ts (1, 2). App rox ima tel y 100 cas es hav e bee n re por ted in pas t lit era tures; how ever, most of the re por ts are foc use d on the ir pa thol ogi c fea tur es (2, 3). Reports of its radiologic characteristics, including computed tomography (CT) and magnetic resonance imaging (MRI), have been still scarce (4–8). We present an unusual case of MEST of the kidney with a polypoid component extending into the renal pelvis and the proximal ureter. Case report A 61-year-old postmenopausal woman presented with gross hema turia for two weeks. The physical examinat ion was unre markable. She had no re leva nt fami ly hi st or y or medical history other than mild obesity. Her routine blood inve stiga tion was normal with no eleva ted serum tumor mar ker . Ultrasonog rap hy re ve ale d the presence of a lef t renal mass in the interpolar region extending into the renal pel vis. Exf olia tiv e urine cyt ology was cla ss 3. Exc re tor y pha se con tra st-enhanced CT (Fig. 1a–c) sho wed a wel l- circumscribed multiseptate cystic mass of 44 Â 40 Â 45 mm in the interpolar region of the left kidney with a polypoid solid component protruding into the renal pelvis and proxi- mal ur ete r. Cal cica tion wa s ide nti ed within the sol id compon ent. Retr ogra de ure tero grap hy (Fig. 1d) showed mild hydrone phros is due to the polypo id part of the tumor in the ureter. Dynamic MRI study (Figs. 2 and 3) demon- strated delayed contrast enhancement of the solid polypoid component and multiple septa. Since the tumor was consistent with a Bosniak category IV cystic mass, we performed a laparoscopic left nephro- ureterectomy. Gross examination showed a well-marginated multilocular cystic mass with a polypoid solid component pr otrudi ng into the re nal pelvis and ureter (Fig. 4a). Histop atholo gical analy sis rev ealed an intermixtur e of epi- thelial elements consisting of varying sized glands and a proli fera tion of spindle cells resembli ng ovar ian stroma. The polyp oi d lesi on wa s supe r ci all y co ve re d wi th normal urothelium. Complex glands with a single layer of atte ned, cuboid or hobnai l-appe aring epithelium and a mild cellular atypia of swollen nuclei were marked in the  Acta Radiologica Short Reports 2012; 1:3. DOI: 10.1258/arsr.2011.110010

Upload: bubblein

Post on 03-Apr-2018

220 views

Category:

Documents


0 download

TRANSCRIPT

Page 1: mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

7/29/2019 mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

http://slidepdf.com/reader/full/mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm 1/5

Case report 

Mixed epithelial and stromal tumor of the kidney with polypoid

component extending into renal pelvis and ureter

Masahiro Horikawa1, Hiroshi Shinmoto1, Kenji Kuroda2, Eisuke Shiomi1, Shigeyoshi Soga1,

Keiichi Ito2, Kazuyoshi Tachi2, Yuka Katsurada3, Hideyuki Simazaki3, Tomohiko Asano2 and

Tatsumi Kaji1

1Department of Radiology; 2Department of Urology; 3Department of Laboratory Medicine, National Defense Medical College, Saitama,

Japan

Correspondence to: Masahiro Horikawa. Email: [email protected]

 Abstract

Mixed epithelial and stromal tumor (MEST) of the kidney is an unusual benign neoplasm that predominantlyoccurs in middle-aged females. It typically appears as a well-circumscribed multiseptate mass with

solid components on computed tomography (CT) or magnetic resonance image (MRI), reflecting its

characteristics of an admixture of stromal proliferation and epithelial cells consisting of multiple cysts. We

present a rare case of 61-year-old woman with MEST, which manifested as a multilocular cystic mass with a

polypoid component protruding into the renal pelvis and ureter. To our best knowledge, this is the first

case of MEST extending into the ureter.

Keywords: Mixed epithelial and stromal tumor, MEST, kidney, ureter, CT, MRI

Submitted October 26, 2011; accepted for publication November 24, 2011

Mixed epithelial and stromal tumor (MEST) is a rare, basi-cally benign neoplasm of the kidney that has recentlybeen recognized as a distinctive entity (1). It mostly occursin middle-aged women and is associated with estrogen exposure (2). The histological characteristic of MEST is an admixture of spindle cells resembling ovarian stroma andepithelial elements (1, 2). Approximately 100 cases havebeen reported in past literatures; however, most of thereports are focused on their pathologic features (2, 3).Reports of its radiologic characteristics, including computed

tomography (CT) and magnetic resonance imaging (MRI),have been still scarce (4–8). We present an unusual case of MEST of the kidney with a polypoid component extendinginto the renal pelvis and the proximal ureter.

Case report

A 61-year-old postmenopausal woman presented with grosshematuria for two weeks. The physical examination wasunremarkable. She had no relevant family history ormedical history other than mild obesity. Her routine bloodinvestigation was normal with no elevated serum tumor

marker. Ultrasonography revealed the presence of a left

renal mass in the interpolar region extending into the renalpelvis. Exfoliative urine cytology was class 3. Excretoryphase contrast-enhanced CT (Fig. 1a– c) showed a well-circumscribed multiseptate cystic mass of 44 Â 40 Â 45 mmin the interpolar region of the left kidney with a polypoidsolid component protruding into the renal pelvis and proxi-mal ureter. Calcification was identified within the solidcomponent. Retrograde ureterography (Fig. 1d) showedmild hydronephrosis due to the polypoid part of the tumorin the ureter. Dynamic MRI study (Figs. 2 and 3) demon-

strated delayed contrast enhancement of the solid polypoidcomponent and multiple septa.

Since the tumor was consistent with a Bosniak categoryIV cystic mass, we performed a laparoscopic left nephro-ureterectomy. Gross examination showed a well-marginatedmultilocular cystic mass with a polypoid solid componentprotruding into the renal pelvis and ureter (Fig. 4a).Histopathological analysis revealed an intermixture of epi-thelial elements consisting of varying sized glands and aproliferation of spindle cells resembling ovarian stroma.The polypoid lesion was superficially covered with normal urothelium. Complex glands with a single layer of flattened, cuboid or hobnail-appearing epithelium and a

mild cellular atypia of swollen nuclei were marked in the

 Acta Radiologica Short Reports 2012;1:3. DOI: 10.1258/arsr.2011.110010

Page 2: mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

7/29/2019 mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

http://slidepdf.com/reader/full/mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm 2/5

Fig. 1 (a) Axial and (b, c) coronal excretory phase contrast CT showing a multilocular cystic mass with a polypoid part continuously extending into the pelvis and

ureter (white arrow); (d) Retrograde ureterography showing a polypoid tumor in the pelvis and proximal ureter and moderate hydronephrosis (white arrow heads)

Fig. 2 (a, b, c, d) Continuous slices of coronal T2-weighted MRI showing a well-circumscribed multiseptate cystic mass with a polypoid compartment extending

into the renal pelvis and proximal ureter 

2 M Horikawa et al.. . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . .

Page 3: mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

7/29/2019 mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

http://slidepdf.com/reader/full/mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm 3/5

Fig. 3 (a) Axial pre-enhanced, (b) axial arterial phase, (c) axial medullary phase fat-saturated T1-weighted MRI. Dynamic MRI study demonstrates delayed

enhancement in the polypoid lesion and septa; (d, e, f) Continuous coronal excretory phase fat-saturated T1-weighted MRI showing marked enhancement in

the polypoid lesion

Fig. 4 (a) Gross specimen showing a cystic lesion with septa and a sharply marginated solid polypoid lesion; (b) Photomicrograph of the polypoid lesion

showing proliferation of stroma, superficially covered with urothelium (black arrow) (hematoxylin and eosin stain;Â200); (c) Low-power-view and (d) high power-

view of the cystic lesion demonstrating an admixture of spindle cells resembling ovarian stroma and epithelial elements consisting of varying sized glands

(c, Â100; d, Â400; hematoxylin and eosin stain)

MEST of the kidney extending into the renal pelvis and ureter  3. . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . .

Page 4: mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

7/29/2019 mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

http://slidepdf.com/reader/full/mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm 4/5

Page 5: mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

7/29/2019 mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm

http://slidepdf.com/reader/full/mmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmmm 5/5

16 Turbiner J, Amin MB, Humphrey PA, et al. Cystic nephroma and mixedepithelial and stromal tumor of kidney: a detailed clinicopathologicanalysis of 34 cases and proposal for renal epithelial and stromal tumor(REST) as a unifying term. Am J Surg Pathol 2007;31:489–500

17 Zhou M, Kort E, Hoekstra P, et al. Adult cystic nephroma and mixedepithelial and stromal tumor of the kidney are the same diseaseentity: molecular and histologic evidence. Am J Surg Pathol2009;33:72–80

# 2012 The Foundation Acta RadiologicaThis is an open-access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by-nc/2.0/), which permits non-commercial use, distribution and reproduction in any medium, provided the original

work is properly cited.

MEST of the kidney extending into the renal pelvis and ureter  5. . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . . .